Riley-Day syndrome

Summary about Disease


Riley-Day syndrome, also known as familial dysautonomia or hereditary sensory and autonomic neuropathy type III (HSAN III), is a rare genetic disorder that primarily affects the development and function of the autonomic nervous system and the sensory nervous system. The autonomic nervous system controls involuntary functions such as heart rate, blood pressure, body temperature, digestion, and sweating. The sensory nervous system is responsible for sensing pain, temperature, and touch. This dysfunction can lead to a wide range of symptoms affecting multiple systems of the body.

Symptoms


Symptoms vary widely in severity and can include:

Feeding difficulties in infancy

Poor weight gain

Lack of tears

Unstable body temperature

Blood pressure instability

Gastrointestinal problems (vomiting crises, constipation)

Pneumonia

Swallowing difficulties

Speech problems

Skeletal abnormalities (scoliosis)

Reduced sensitivity to pain and temperature

Absent or diminished reflexes

Drooling

Emotional lability

Causes


Riley-Day syndrome is caused by mutations in the ELP1 gene (also known as *IKBKAP*) located on chromosome 9. This gene provides instructions for making a protein called Elongator complex protein 1, which is involved in nerve cell development and function. The mutations lead to a reduced amount of functional Elongator complex protein 1, disrupting the normal development and function of the nervous system. It is inherited in an autosomal recessive pattern, meaning both parents must carry a copy of the mutated gene for their child to be affected.

Medicine Used


There is no cure for Riley-Day syndrome. Treatment is focused on managing individual symptoms and improving quality of life. Medications may include:

Medications to manage blood pressure (e.g., beta-blockers, fludrocortisone)

Anti-reflux medications for gastrointestinal issues

Laxatives for constipation

Antibiotics for infections

Sedatives for vomiting crisis

Is Communicable


No, Riley-Day syndrome is not communicable. It is a genetic disorder and cannot be spread from person to person.

Precautions


Precautions for individuals with Riley-Day syndrome and their caregivers include:

Careful monitoring of vital signs (temperature, blood pressure, heart rate)

Preventing dehydration and overheating

Protecting from injury due to reduced pain sensitivity

Managing feeding difficulties and ensuring adequate nutrition

Preventing aspiration during feeding

Regular monitoring by a multidisciplinary team of healthcare professionals

How long does an outbreak last?


There are no "outbreaks" associated with Riley-Day syndrome. The condition is chronic and lifelong, requiring ongoing management of symptoms. A vomiting crisis or other symptom exacerbations may occur acutely and last hours to days, requiring specific medical intervention.

How is it diagnosed?


Diagnosis typically involves:

Clinical evaluation based on the presence of characteristic symptoms.

Genetic testing to identify mutations in the ELP1 gene.

Histamine skin test (reduced or absent flare response).

Neurological examination.

Tear production test (Schirmer test).

Timeline of Symptoms


Symptoms often manifest in infancy or early childhood.

Infancy: Feeding difficulties, poor weight gain, lack of tears, temperature instability.

Early Childhood: Vomiting crises, pneumonia, developmental delays, speech problems.

Childhood/Adolescence: Scoliosis, blood pressure instability, gastrointestinal issues.

Throughout Life: Symptoms persist and require ongoing management.

Important Considerations


Riley-Day syndrome requires comprehensive, multidisciplinary care from specialists familiar with the condition.

Early diagnosis and intervention are crucial for improving outcomes.

Genetic counseling is recommended for families with a history of the disorder.

Support groups and advocacy organizations can provide valuable resources and information.

Research is ongoing to better understand the disorder and develop new treatments.